RecruitingPhase 2NCT07123155

Study of S-606001 as an Add-on to Enzyme Replacement Therapy (ERT) in Participants With Late-onset Pompe Disease (LOPD)

A Phase 2, Multicenter, Randomized, Placebo-controlled, Double-blind Study to Investigate the Safety, Pharmacodynamics, and Preliminary Efficacy of S-606001 as an Add-on to Enzyme Replacement Therapy in Patients With Late-onset Pompe Disease


Sponsor

Shionogi

Enrollment

45 participants

Start Date

Oct 30, 2025

Study Type

INTERVENTIONAL

Conditions

Summary

The purpose of this study is to evaluate the safety, pharmacodynamics (PD), and exploratory clinical efficacy of S-606001 in adult participants with LOPD as an add-on to ERT.


Eligibility

Min Age: 18 Years

Inclusion Criteria9

  • Participant must be ≥18 years of age and ≥40 kilograms (kg) of body weight at the time of signing the informed consent.
  • Participant must have a diagnosis of LOPD based on documentation of 1 of the following:
  • Deficiency of acid alpha-glucosidase (GAA) enzyme
  • GAA genotype
  • Participant has a %FVC ≥30% and ≤80% in an upright position without mechanical ventilation at screening; or Participant has ≥10% %FVC drop from upright position to supine position and %FVC ≥20% in a supine position.
  • Participant performs the 6MWT at screening, as determined by the clinical evaluator, and meets all of the following criteria:
  • Screening values of 6-minute walk distance (6MWD) are ≥75 meters
  • Screening values of 6MWD are ≤90% of the predicted value for healthy adults
  • Participants must be ERT-experienced, defined as currently receiving ERT and having been receiving ERT for ≥24 months, with no regimen change in the last 6 months.

Exclusion Criteria9

  • Has a medical condition or any other extenuating circumstance that may pose an undue safety risk to the participant or may compromise his/her ability to comply with or adversely impact protocol requirements.
  • Has active infections at screening.
  • Malignancy within the past 5 years except for basal cell or squamous epithelial carcinomas of the skin that have been resected with no evidence of metastatic disease for 3 years.
  • Current or chronic history of liver disease.
  • Known biallelic loss of function mutations whether in glycogenin gene (GYG) or in glycogen phosphorylase muscle associated gene(PYGM) .
  • Has received any investigational therapy or pharmacological treatment for Pompe disease, within 30 days or 5 half-lives of the therapy or treatment, whichever is longer, before day 1 or is anticipated to do so during the study.
  • Has received gene therapy or small interfering ribonucleic acid (RNA) therapy for Pompe disease.
  • Participant, if female, is pregnant or breastfeeding at screening.
  • Participant, whether male or female, is planning to conceive a child during the study.

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Interventions

DRUGS-606001

S-606001 administered orally

DRUGPlacebo

S-606001 matching placebo administered orally


Locations(28)

University of California - Irvine Medical Center

Irvine, California, United States

University of Florida (UF) - Gainesville

Gainesville, Florida, United States

Emory University Hospital

Atlanta, Georgia, United States

Washington University in St. Louis

St Louis, Missouri, United States

Duke University Medical Center

Durham, North Carolina, United States

Cincinnati Children's Hospital Medical Center

Cincinnati, Ohio, United States

University of Pennsylvania

Philadelphia, Pennsylvania, United States

University of Pittsburgh School of Medicine

Pittsburgh, Pennsylvania, United States

Lysosomal and Rare Disorders Research and Treatment Center (LDRTC)

Fairfax, Virginia, United States

UZ Leuven

Leuven, Belgium

Aarhus University Hospital

Aarhus, Denmark

HLC Hopital Pierre Wertheimer

Bron, France

AP-HP Hopital Raymond Poincare

Garches, France

Centre de Reference des Maladies Neuromusculaires et de la SLA - AP-HM Hopital de La Timone

Marseille, France

CHU de Nice - Hopital Pasteur 2 - Centre de reference des Maladies Neuromusculaires

Nice, France

Universitaetsklinikum Halle (Saale)

Halle, Germany

SphinCS GmbH

Höchheim, Germany

Klinikum der Ludwig-Maximilians-Universitaet Muenchen

München, Germany

A.O.U. Policlinico "G. Martino"

Messina, Italy

AOU Citta della Salute e della Scienza di Torino - Ospedale le Molinette

Torino, Italy

Erasmus MC

GE Rotterdam, GE Rotterdam, Netherlands

Hospital Universitario 12 de Octubre

Madrid, Spain

Hospital Universitari i Politecnic La Fe

Valencia, Spain

Salford Royal Hospital

Statford, Statford, United Kingdom

Queen Elizabeth Hospital Birmingham

Birmingham, United Kingdom

National Hospital for Neurology & Neurosurgery

London, United Kingdom

Royal Free London NHS Foundation Trust

London, United Kingdom

Royal Victoria Infirmary

Newcastle upon Tyne, United Kingdom

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NCT07123155


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