RecruitingPhase 2Phase 3NCT04987463

Efficacy and Safety of Rapamycin Versus Vigabatrin in the Prevention of Tuberous Sclerosis Complex Symptoms in Infants

Randomized, Placebo-controlled, Double-blind and Double-dummy Clinical Trial Comparing the Safety, Tolerability, and Efficacy of Vigabatrin and Rapamycin in a Preventive Treatment of Infants With Tuberous Sclerosis Complex


Sponsor

Katarzyna Kotulska

Enrollment

60 participants

Start Date

May 7, 2021

Study Type

INTERVENTIONAL

Conditions

Summary

The purpose of the study is to evaluate the efficacy, tolerability, and safety of vigabatrin versus rapamycin as a preventive treatment in infants with Tuberous Sclerosis Complex (TSC).


Eligibility

Min Age: 4 WeeksMax Age: 16 Weeks

Inclusion Criteria5

  • Male or female aged from 4 up to 16 weeks (44-56 weeks of gestational age) at the day of randomization
  • Parents/caregivers are willing to and able to give informed consent form for the participation in the study
  • Parents/caregivers are willing to and able to comply with all study requirements
  • Definite diagnosis of TSC according to the Consensus criteria (Northrup,2013)
  • At least 1 focus of cortical dysplasia disclosed on brain MRI

Exclusion Criteria13

  • history of seizures prior to randomization,
  • history of antiepileptic treatment,
  • history of treatment with mTOR (mammalian Target of Rapamycin) inhibitor,
  • gestational age below 44 weeks at the day of randomization,
  • body weight lower than 3 kg at the day of randomization,
  • SEGA (Subependymal Giant Cell Astrocytoma) or other TSC-associated lesion requiring urgent surgical intervention
  • recent surgery within 1 month prior to the randomization
  • intercurrent infection at the date of randomization
  • known history of HIV seropositivity
  • live vaccination within 1 month prior to randomization\*
  • lack of first TBC and hepatitis B vaccinations
  • Any significant clinical, laboratory , ECG or other abnormalities, comorbidity or concomitant treatment which, in the opinion of the investigator, may either put a patient at significant risk associated with the participation in the study or may influence the results of the study.
  • Use of an investigational drug within 1 month prior to randomization.

Interventions

DRUGVigabatrin

Vigabatrin in capsules administered orally, initially (between V1 and V2) once daily in the evening,and starting from V2 administered two times daily.

DRUGRapamycin

Rapamycin in liquid administered orally, in the morning, every other day or daily depending on the patient's body weight. The starting dose of rapamycin will be calculated according to the body weight of the patient measured at V1.

DRUGPlacebo

Placebo in liquid administered orally, once daily, in the morning. The starting dose of placebo in liquid will be calculated according to the body weight of the patient measured at V1.

DRUGPlacebo

Placebo in granules administered orally, initially once daily in the evening,and after reaching the targeted dose administered two times daily.


Locations(2)

Medical University of Warsaw, Department of Pediatric Neurology

Warsaw, Poland

Children's Memorial Health Institute, Neurology and Epileptology

Warsaw, Poland

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NCT04987463


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